603592
XANTHINURIA, TYPE II

Alternative titles; symbols
XANTHINE DEHYDROGENASE AND ALDEHYDE OXIDASE, COMBINED DEFICIENCY OF

TEXT
Two clinically similar but distinct forms of xanthinuria are recognized. In type I xanthinuria (278300), there is an isolated deficiency of xanthine dehydrogenase; in type II, there is a dual deficiency of xanthine dehydrogenase and aldehyde oxidase. Type I patients can metabolize allopurinol, whereas type II patients cannot (Simmonds et al., 1995).

Beaudet (1999) indicated that the mutation in type II xanthinuria may not be in the structural gene for either xanthine dehydrogenase or aldehyde oxidase, but possibly in the mechanism responsible for inserting the essential sulfur atom into the active center of both enzymes.

REFERENCES
1. Beaudet, A. L. Personal Communication. Houston, Tex. 2/15/1999.

2. Simmonds, H. A., Reiter, S., Nishino, T. Hereditary xanthinuria.In: Scriver, C. R.; Beaudet, A. L.; Sly, W. S.; Valle, D. (eds.) : The Metabolic and Molecular Bases of Inherited Disease. Vol. 2 New York: McGraw-Hill 1995. P. 1781.

Creation Date: Ada Hamosh : 2/26/1999
Edit History: mgross : 03/18/2003
mgross : 3/18/2003
carol : 2/26/1999